Orfadin 4mg/ml Suspension

Manufacturer SOBI Active Ingredient Nitisinone Oral Suspension(ni TIS i known) Pronunciation ni TIS i known
It is used to treat hereditary tyrosinemia type 1 (HT-1).
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Drug Class
Enzyme inhibitor, Tyrosinemia Type 1 treatment
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Pharmacologic Class
4-hydroxyphenylpyruvate dioxygenase (HPPD) inhibitor
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Pregnancy Category
Category C
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FDA Approved
Jan 1997
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DEA Schedule
Not Controlled

Overview

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What is this medicine?

Nitisinone is a medicine used to treat a rare genetic disease called hereditary tyrosinemia type 1 (HT-1). In this disease, the body cannot properly break down a substance called tyrosine, leading to the buildup of harmful toxins. Nitisinone works by blocking an enzyme in the body, which helps prevent these toxins from forming. This helps protect the liver, kidneys, and nervous system from damage.
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How to Use This Medicine

Taking Your Medication

To use this medication correctly, follow your doctor's instructions and read all the information provided. If the adapter is not already attached to the bottle, prepare it according to the instructions you received or as described in the package insert. You can take this medication with or without food.

Before each use, shake the bottle well for at least 5 seconds to ensure the particles are fully dissolved. To measure the correct dose, use the measuring device that comes with the medication. If one is not provided, ask your pharmacist for a suitable measuring device.

Continue taking this medication as directed by your doctor or healthcare provider, even if you start to feel better.

Storing and Disposing of Your Medication

If the adapter is not attached to the bottle when you receive it, store the bottle in the refrigerator until you are ready to prepare it. Do not freeze the medication.

Once the adapter is attached, store the bottle at room temperature (up to 77°F or 25°C).

What to Do If You Miss a Dose

If you miss a dose, take it as soon as you remember. However, if it is close to the time for your next scheduled dose, skip the missed dose and resume your regular dosing schedule. Do not take two doses at the same time or take extra doses.
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Lifestyle & Tips

  • Strict adherence to a low-tyrosine and low-phenylalanine diet is crucial for the effectiveness of nitisinone and to prevent complications like hypertyrosinemia. Dietary management should be supervised by a metabolic dietitian.
  • Regular follow-up appointments and blood tests are essential to monitor drug levels, tyrosine levels, and overall health.
  • Report any new or worsening symptoms, especially eye problems (like sensitivity to light, eye pain, or blurred vision), skin rashes, or signs of infection/bleeding.

Dosing & Administration

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Adult Dosing

Standard Dose: 0.5 mg/kg orally once daily, adjusted based on succinylacetone and tyrosine levels.
Dose Range: 0.5 - 2 mg

Condition-Specific Dosing:

Hereditary Tyrosinemia Type 1 (HT-1): Initial dose 0.5 mg/kg/day. Adjust dose to achieve undetectable plasma succinylacetone levels and plasma tyrosine levels below 500 micromol/L. Maximum dose is 2 mg/kg/day.
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Pediatric Dosing

Neonatal: 0.5 mg/kg orally once daily, adjusted based on succinylacetone and tyrosine levels. Treatment should be initiated as soon as HT-1 is diagnosed.
Infant: 0.5 mg/kg orally once daily, adjusted based on succinylacetone and tyrosine levels. Treatment should be initiated as soon as HT-1 is diagnosed.
Child: 0.5 mg/kg orally once daily, adjusted based on succinylacetone and tyrosine levels. Maximum dose is 2 mg/kg/day.
Adolescent: 0.5 mg/kg orally once daily, adjusted based on succinylacetone and tyrosine levels. Maximum dose is 2 mg/kg/day.
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Dose Adjustments

Renal Impairment:

Mild: No specific dose adjustment recommended.
Moderate: No specific dose adjustment recommended.
Severe: Use with caution; no specific dose recommendations available. Monitor closely for adverse effects.
Dialysis: Not available. Nitisinone is highly protein bound, so dialysis is unlikely to be effective for removal.

Hepatic Impairment:

Mild: No specific dose adjustment recommended.
Moderate: No specific dose adjustment recommended.
Severe: Use with caution; no specific dose recommendations available. Monitor closely for adverse effects, especially in patients with severe liver disease due to HT-1.

Pharmacology

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Mechanism of Action

Nitisinone is a competitive inhibitor of 4-hydroxyphenylpyruvate dioxygenase (HPPD), an enzyme in the tyrosine catabolic pathway. By inhibiting HPPD, nitisinone prevents the formation of maleylacetoacetate and fumarylacetoacetate, and subsequently succinylacetone, which is a highly toxic metabolite that accumulates in patients with hereditary tyrosinemia type 1 (HT-1). This inhibition reduces the accumulation of toxic metabolites, thereby preventing liver and kidney damage, neurological crises, and hepatocellular carcinoma associated with HT-1.
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Pharmacokinetics

Absorption:

Bioavailability: Not explicitly quantified, but well absorbed.
Tmax: Approximately 3 hours (range 2-6 hours)
FoodEffect: A high-fat meal can delay Tmax by approximately 2 hours but does not significantly affect the extent of absorption (AUC).

Distribution:

Vd: Approximately 1 L/kg
ProteinBinding: >99% (primarily to albumin)
CnssPenetration: Limited

Elimination:

HalfLife: Approximately 54 hours (range 36-90 hours)
Clearance: Not available
ExcretionRoute: Primarily renal (as metabolites)
Unchanged: <1% (in urine)
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Pharmacodynamics

OnsetOfAction: Reduction in succinylacetone levels typically observed within days to weeks.
PeakEffect: Stabilization of succinylacetone and tyrosine levels typically achieved within weeks to months of dose titration.
DurationOfAction: Due to long half-life, once-daily dosing is sufficient to maintain therapeutic levels.

Safety & Warnings

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Side Effects

Urgent Side Effects: Seek Medical Attention Immediately

Although rare, some people may experience severe and potentially life-threatening side effects while taking this medication. If you notice any of the following symptoms, contact your doctor or seek medical help right away:

Signs of an allergic reaction, such as:
+ Rash
+ Hives
+ Itching
+ Red, swollen, blistered, or peeling skin with or without fever
+ Wheezing
+ Tightness in the chest or throat
+ Trouble breathing, swallowing, or talking
+ Unusual hoarseness
+ Swelling of the mouth, face, lips, tongue, or throat
Signs of liver problems, including:
+ Dark urine
+ Tiredness
+ Decreased appetite
+ Upset stomach or stomach pain
+ Light-colored stools
+ Vomiting
+ Yellow skin or eyes
Changes in eyesight, eye pain, or severe eye irritation
Sensitivity to bright light
Confusion, difficulty focusing, or changes in behavior
Redness, irritation, pain, or thick skin on the palms of the hands or soles of the feet
Signs of infection, such as:
+ Fever
+ Chills
+ Sore throat (due to low white blood cell counts, which may increase the risk of infection)
Unexplained bruising or bleeding (due to low platelet counts, which may increase the risk of bleeding)

Other Possible Side Effects

Most people taking this medication will not experience side effects, or they will be mild. However, if you notice any of the following side effects or any other unusual symptoms, contact your doctor or seek medical help:

Headache
Upset stomach
* Diarrhea

This is not an exhaustive list of possible side effects. If you have questions or concerns about side effects, consult your doctor. You can also report side effects to the FDA at 1-800-332-1088 or online at https://www.fda.gov/medwatch.
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Seek Immediate Medical Attention If You Experience:

  • Eye pain, redness, or sensitivity to light (photophobia)
  • Blurred vision or changes in vision
  • Skin rash or lesions (especially on palms and soles)
  • Unexplained bruising or bleeding
  • Unusual tiredness or weakness
  • Signs of infection (fever, sore throat)
  • Yellowing of skin or eyes (jaundice)
  • Swelling in the abdomen or legs
  • Changes in behavior or neurological symptoms (e.g., numbness, tingling, weakness)
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Before Using This Medicine

Before Taking This Medication: Important Information to Share with Your Doctor

It is essential to inform your doctor about the following:

Any allergies you have, including allergies to this medication, its components, or other substances, such as foods or drugs. Be sure to describe the allergic reaction you experienced, including any symptoms that occurred.
All medications you are currently taking, including prescription and over-the-counter (OTC) drugs, natural products, and vitamins. This is crucial to ensure safe use and avoid potential interactions.
* Any existing health problems, as this medication may interact with other medical conditions.

To guarantee your safety, carefully review all your medications and health issues with your doctor and pharmacist. Never start, stop, or adjust the dosage of any medication without first consulting your doctor to confirm it is safe to do so.
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Precautions & Cautions

It is essential to inform all your healthcare providers, including doctors, nurses, pharmacists, and dentists, that you are taking this medication.

Regular blood tests will be necessary, as directed by your doctor, to monitor your condition. Be sure to discuss any concerns or questions you have with your doctor regarding these tests.

Additionally, your doctor may require you to have your urine checked periodically. It is crucial to follow your doctor's instructions for urine testing.

An eye exam may also be necessary, as scheduled by your doctor, to assess any potential effects of the medication on your vision.

To maximize the benefits of this medication, it is vital to adhere to the diet plan recommended by your doctor.

If you are pregnant, planning to become pregnant, or are breastfeeding, you must notify your doctor. Your doctor will discuss the potential benefits and risks of taking this medication during pregnancy or breastfeeding, allowing you to make an informed decision about your care and the well-being of your baby.
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Overdose Information

Overdose Symptoms:

  • Exaggerated adverse effects, particularly severe hypertyrosinemia with associated ocular symptoms (corneal opacities, photophobia, keratitis), skin lesions, and neurological symptoms.
  • Increased risk of myelosuppression (leukopenia, thrombocytopenia).

What to Do:

There is no specific antidote for nitisinone overdose. Management should be supportive and symptomatic. Discontinue nitisinone and monitor plasma tyrosine and succinylacetone levels, CBC, liver and renal function. Consult a poison control center (Call 1-800-222-1222 in the US) or emergency medical services immediately.

Drug Interactions

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Moderate Interactions

  • Drugs that significantly induce or inhibit CYP3A4 or CYP2C9 (monitor nitisinone levels and adjust dose if necessary).
  • Drugs that cause myelosuppression (e.g., chemotherapy, immunosuppressants) - increased risk of leukopenia/thrombocytopenia.
  • Drugs that can cause ocular toxicity (e.g., amiodarone, chloroquine) - potential additive risk of ocular adverse effects, especially with elevated tyrosine levels.

Monitoring

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Baseline Monitoring

Plasma succinylacetone levels

Rationale: To establish baseline and guide initial dose titration.

Timing: Prior to initiation of therapy.

Plasma tyrosine levels

Rationale: To establish baseline and guide initial dose titration, and to monitor for hypertyrosinemia.

Timing: Prior to initiation of therapy.

Liver function tests (ALT, AST, bilirubin, albumin, INR)

Rationale: To assess baseline liver function and monitor for potential hepatotoxicity.

Timing: Prior to initiation of therapy.

Renal function tests (BUN, creatinine)

Rationale: To assess baseline renal function.

Timing: Prior to initiation of therapy.

Complete Blood Count (CBC) with differential and platelets

Rationale: To assess baseline hematologic status and monitor for myelosuppression.

Timing: Prior to initiation of therapy.

Ophthalmologic examination (slit lamp, visual acuity)

Rationale: To establish baseline ocular health and monitor for tyrosine-induced ocular toxicity.

Timing: Prior to initiation of therapy.

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Routine Monitoring

Plasma succinylacetone levels

Frequency: Weekly during initial dose titration, then monthly or as clinically indicated once stable.

Target: Undetectable

Action Threshold: If detectable, consider dose increase or adherence issues.

Plasma tyrosine levels

Frequency: Weekly during initial dose titration, then monthly or as clinically indicated once stable.

Target: < 500 micromol/L

Action Threshold: If > 500 micromol/L, consider dose reduction, dietary adherence, or other causes.

Liver function tests (ALT, AST, bilirubin, albumin, INR)

Frequency: Monthly for the first few months, then every 3-6 months or as clinically indicated.

Target: Within normal limits

Action Threshold: Significant elevations may require dose adjustment or investigation.

Complete Blood Count (CBC) with differential and platelets

Frequency: Monthly for the first few months, then every 3-6 months or as clinically indicated.

Target: Within normal limits

Action Threshold: Significant decreases (e.g., leukopenia, thrombocytopenia) may require dose adjustment or investigation.

Ophthalmologic examination

Frequency: Every 6-12 months, or more frequently if ocular symptoms develop or tyrosine levels are persistently high.

Target: Normal ocular findings

Action Threshold: Development of corneal opacities, photophobia, or other ocular symptoms requires immediate evaluation and potential dose adjustment/dietary review.

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Symptom Monitoring

  • Changes in vision (e.g., photophobia, eye pain, blurred vision)
  • Skin rash or lesions
  • Unexplained bleeding or bruising (signs of thrombocytopenia)
  • Frequent infections (signs of leukopenia)
  • Neurological symptoms (e.g., peripheral neuropathy, developmental regression)
  • Signs of liver dysfunction (e.g., jaundice, ascites, easy bruising)

Special Patient Groups

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Pregnancy

Nitisinone is classified as Pregnancy Category C. Animal studies have shown adverse effects on fetal development (e.g., skeletal abnormalities, reduced fetal weight) at doses higher than human therapeutic doses. There are no adequate and well-controlled studies in pregnant women. Nitisinone should be used during pregnancy only if the potential benefit justifies the potential risk to the fetus. Untreated HT-1 in the mother can also pose significant risks to both mother and fetus.

Trimester-Specific Risks:

First Trimester: Potential for teratogenicity observed in animal studies. Risk to human fetus unknown but cannot be ruled out.
Second Trimester: Potential for adverse developmental effects.
Third Trimester: Potential for adverse developmental effects.
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Lactation

It is not known whether nitisinone is excreted in human milk. Due to the potential for serious adverse reactions in a breastfed infant, a decision should be made whether to discontinue breastfeeding or to discontinue the drug, taking into account the importance of the drug to the mother and the potential risks to the infant. The long half-life of nitisinone suggests potential for accumulation in breast milk.

Infant Risk: Risk unknown, but potential for serious adverse effects (e.g., tyrosine-related toxicity) exists. Caution advised.
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Pediatric Use

Nitisinone is indicated for pediatric patients with HT-1. Dosing is weight-based and adjusted based on biochemical markers. Early initiation of therapy is crucial to prevent irreversible organ damage. Long-term safety and efficacy have been established in this population.

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Geriatric Use

Clinical studies of nitisinone did not include sufficient numbers of subjects aged 65 and over to determine whether they respond differently from younger subjects. In general, dose selection for an elderly patient should be cautious, usually starting at the low end of the dosing range, reflecting the greater frequency of decreased hepatic, renal, or cardiac function, and of concomitant disease or other drug therapy. However, HT-1 is typically diagnosed and managed from infancy, so geriatric patients are rare.

Clinical Information

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Clinical Pearls

  • Nitisinone therapy must always be accompanied by a strict low-tyrosine and low-phenylalanine diet to prevent hypertyrosinemia and its associated complications (e.g., ocular toxicity, neurological symptoms).
  • Regular monitoring of plasma succinylacetone (target undetectable) and tyrosine (target < 500 micromol/L) levels is critical for effective dose titration and management.
  • Ophthalmologic examinations are essential due to the risk of tyrosine-induced ocular toxicity (corneal opacities, photophobia, keratitis).
  • Patients should be educated on the importance of adherence to both medication and diet, and to report any new or worsening symptoms promptly.
  • Nitisinone is an orphan drug, and patient assistance programs are often available to help with the high cost.
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Alternative Therapies

  • Dietary management (low-tyrosine, low-phenylalanine diet) is a cornerstone of HT-1 treatment, always used in conjunction with nitisinone.
  • Liver transplantation: Considered for patients who fail to respond to nitisinone therapy, develop hepatocellular carcinoma, or have severe liver disease despite treatment. It is a curative option for the liver disease but does not address renal or neurological complications as effectively as nitisinone.
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Cost & Coverage

Average Cost: Highly variable, typically very expensive per bottle/capsule
Generic Available: Yes
Insurance Coverage: Specialty Tier (requires prior authorization and often strict adherence to medical necessity criteria)
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General Drug Facts

If your symptoms or health issues persist or worsen, it's essential to contact your doctor for further guidance. To ensure your safety, never share your medication with others or take someone else's medication. Some medications may come with an additional patient information leaflet, so be sure to check with your pharmacist for more information. If you have any questions or concerns about your medication, don't hesitate to reach out to your doctor, nurse, pharmacist, or other healthcare provider. In the event of a suspected overdose, immediately call your local poison control center or seek emergency medical attention. When seeking help, be prepared to provide details about the medication taken, the amount, and the time it happened.